Epidermoid cyst, a variant of dermoid cyst, is a benign lesion of epithelial origin, in which the cystic cavity is lined by epithelium without skin appendages. The head and neck sites most commonly affected with cutaneous cysts include the scalp (34%), neck (18%), periorbital area (17%), cheeks (including lips-16%), periauricular area (9%), and nasal area (including forehead-6%). Although a common cutaneous presentation in the head and neck region, epidermoid cysts of the maxillary sinus is an extremely rare occurrence. We report a case of epidermoid cyst of the maxillary sinus. The lesion being rare and asymptomatic often presents a diagnostic dilemma for the clinician.